ERJ Open Research (Dec 2024)
Acute exacerbations in patients with progressive pulmonary fibrosis
- Michael Kreuter,
- Elizabeth A. Belloli,
- Elisabeth Bendstrup,
- Stefania Cerri,
- Kevin R. Flaherty,
- Shane Shapera,
- Jin Woo Song,
- Heiko Mueller,
- Klaus B. Rohr,
- Yasuhiro Kondoh,
- on behalf of the INBUILD trial investigators,
- S. Quadrelli,
- M. Otaola,
- M.A. Bergna,
- P. Elias,
- G. Arce,
- A. Cazaux,
- J. Guiot,
- B. Bondue,
- C. Dahlqvist,
- L. Homik,
- S. Shapera,
- A. Cantin,
- M. Kolb,
- M. Salinas Fénero,
- R. Maturana Rozas,
- A. Silva Orellana,
- Z. Xu,
- Q. Luo,
- J. Kang,
- H. Cai,
- S. Marchand-Adam,
- E. Bergot,
- A. Gamez-Dubuis,
- F. Riviere,
- R. Kessler,
- H. Nunes,
- C. Marquette,
- L. Wemeau,
- S. Jouneau,
- F. Lebargy,
- B. Crestani,
- V. Cottin,
- M. Reynaud-Gaubert,
- S. Blaas,
- F. Bonella,
- W. Randerath,
- J. Hetzel,
- D. Koschel,
- M. Kreuter,
- A. Prasse,
- D. Skowasch,
- S. Stieglitz,
- R. Refini,
- S. Cerri,
- A. Pesci,
- S. Tomassetti,
- C. Vancheri,
- F. Varone,
- N. Sakamoto,
- S. Abe,
- H. Hayashi,
- T. Saito,
- T. Suda,
- H. Kitamura,
- M. Okamoto,
- Y. Kondoh,
- S. Makino,
- T. Takeuchi,
- Y. Yamada,
- C. Kono,
- Y. Inoue,
- H. Sugiura,
- K. Kishi,
- H. Takaya,
- H. Yamauchi,
- K. Ichikado,
- K. Tomii,
- H. Takahashi,
- S. Izumi,
- T. Kawamura,
- Y. Nishioka,
- Y. Miyazaki,
- J.W. Song,
- J.S. Park,
- Y. Kim,
- E. Jassem,
- J. Kus,
- W. Piotrowski,
- A. Barczyk,
- D. Ziora,
- E. Bazdyrev,
- S. Moiseev,
- S. Avdeev,
- M. Ilkovich,
- V. Yakusevich,
- C. Valenzuela,
- O. Acosta,
- M. Martínez,
- L. Gómez,
- M. Molina-Molina,
- D.M. Castillo Villegas,
- M. Aburto,
- J.A. Rodríguez Portal,
- A. Villar,
- A. León Jiménez,
- J. Sauleda,
- M. Arias,
- P. Beirne,
- H. Stone,
- B. Hope-Gill,
- N. Hirani,
- N. Chaudhuri,
- A. Gifford,
- L. Jones,
- L. Morrison,
- D. Antin-Ozerkis,
- N. Bhatt,
- T. Kulkarni,
- T. Moua,
- N. Ettinger,
- L. Pitts,
- S. Veeraraghavan,
- M. Padilla,
- E.R. Fernández Pérez,
- G. Giessel,
- M. Strek,
- S. Danoff,
- J. Burk,
- M. Rossman,
- N. Patel,
- E. Belloli,
- D. Hotchkin,
- S. Weigt,
- M.B. Scholand,
- R. Kaner,
- B. Sigal,
- Z. Safdar,
- L. Tolle,
- R. Martinez,
- M. Glassberg,
- R. Hallowell,
- J. Golden,
- M. Schwartz,
- E. Britt,
- L. Morrow,
- Y. Mageto,
- K. Buch,
- S. Chaaban,
- H. Poonyagariyagorn,
- D. Dilling,
- O. Shlobin,
- K. Thavarajah,
- A. Nambiar,
- I. Rosas,
- R. Bascom,
- J. Oldham,
- S. Schmidt,
- J. Dematte D'Amico,
- J. Falk,
- C. Glazer,
- G. Criner
Affiliations
- Michael Kreuter
- Center for Pulmonary Medicine, Department of Pneumology, Mainz University Medical Center and Pulmonary, Critical Care & Sleep Medicine, Marienhaus Clinic Mainz, Mainz, Germany
- Elizabeth A. Belloli
- Division of Pulmonary and Critical Care Medicine, University of Michigan, Ann Arbor, MI, USA
- Elisabeth Bendstrup
- Department of Respiratory Diseases and Allergy, Centre for Rare Lung Diseases, Aarhus University Hospital, Aarhus, Denmark
- Stefania Cerri
- Center for Rare Lung Disease – Azienda Ospedaliero-Universitaria Policlinico di Modena, Modena, Italy
- Kevin R. Flaherty
- Division of Pulmonary and Critical Care Medicine, University of Michigan, Ann Arbor, MI, USA
- Shane Shapera
- Division of Respirology, University Health Network, University of Toronto, Toronto, ON, Canada
- Jin Woo Song
- Department of Pulmonary and Critical Care Medicine, Asan Medical Center, Seoul, South Korea
- Heiko Mueller
- Boehringer Ingelheim Pharma GmbH & Co. KG, Ingelheim am Rhein, Germany
- Klaus B. Rohr
- Boehringer Ingelheim International GmbH, Ingelheim am Rhein, Germany
- Yasuhiro Kondoh
- Department of Respiratory Medicine and Allergy, Tosei General Hospital, Japan
- on behalf of the INBUILD trial investigators
- For a list of the INBUILD trial investigators and their affiliations, see the Acknowledgements
- S. Quadrelli
- M. Otaola
- M.A. Bergna
- P. Elias
- G. Arce
- A. Cazaux
- J. Guiot
- B. Bondue
- C. Dahlqvist
- L. Homik
- S. Shapera
- A. Cantin
- M. Kolb
- M. Salinas Fénero
- R. Maturana Rozas
- A. Silva Orellana
- Z. Xu
- Q. Luo
- J. Kang
- H. Cai
- S. Marchand-Adam
- E. Bergot
- A. Gamez-Dubuis
- F. Riviere
- R. Kessler
- H. Nunes
- C. Marquette
- L. Wemeau
- S. Jouneau
- F. Lebargy
- B. Crestani
- V. Cottin
- M. Reynaud-Gaubert
- S. Blaas
- F. Bonella
- W. Randerath
- J. Hetzel
- D. Koschel
- M. Kreuter
- A. Prasse
- D. Skowasch
- S. Stieglitz
- R. Refini
- S. Cerri
- A. Pesci
- S. Tomassetti
- C. Vancheri
- F. Varone
- N. Sakamoto
- S. Abe
- H. Hayashi
- T. Saito
- T. Suda
- H. Kitamura
- M. Okamoto
- Y. Kondoh
- S. Makino
- T. Takeuchi
- Y. Yamada
- C. Kono
- Y. Inoue
- H. Sugiura
- K. Kishi
- H. Takaya
- H. Yamauchi
- K. Ichikado
- K. Tomii
- H. Takahashi
- S. Izumi
- T. Kawamura
- Y. Nishioka
- Y. Miyazaki
- J.W. Song
- J.S. Park
- Y. Kim
- E. Jassem
- J. Kus
- W. Piotrowski
- A. Barczyk
- D. Ziora
- E. Bazdyrev
- S. Moiseev
- S. Avdeev
- M. Ilkovich
- V. Yakusevich
- C. Valenzuela
- O. Acosta
- M. Martínez
- L. Gómez
- M. Molina-Molina
- D.M. Castillo Villegas
- M. Aburto
- J.A. Rodríguez Portal
- A. Villar
- A. León Jiménez
- J. Sauleda
- M. Arias
- P. Beirne
- H. Stone
- B. Hope-Gill
- N. Hirani
- N. Chaudhuri
- A. Gifford
- L. Jones
- L. Morrison
- D. Antin-Ozerkis
- N. Bhatt
- T. Kulkarni
- T. Moua
- N. Ettinger
- L. Pitts
- S. Veeraraghavan
- M. Padilla
- E.R. Fernández Pérez
- G. Giessel
- M. Strek
- S. Danoff
- J. Burk
- M. Rossman
- N. Patel
- E. Belloli
- D. Hotchkin
- S. Weigt
- M.B. Scholand
- R. Kaner
- B. Sigal
- Z. Safdar
- L. Tolle
- R. Martinez
- M. Glassberg
- R. Hallowell
- J. Golden
- M. Schwartz
- E. Britt
- L. Morrow
- Y. Mageto
- K. Buch
- S. Chaaban
- H. Poonyagariyagorn
- D. Dilling
- O. Shlobin
- K. Thavarajah
- A. Nambiar
- I. Rosas
- R. Bascom
- J. Oldham
- S. Schmidt
- J. Dematte D'Amico
- J. Falk
- C. Glazer
- G. Criner
- DOI
- https://doi.org/10.1183/23120541.00403-2024
- Journal volume & issue
-
Vol. 10,
no. 6
Abstract
Background Acute exacerbations of fibrosing interstitial lung diseases (ILDs) are associated with high mortality. We used prospective data from the INBUILD trial to investigate risk factors for acute exacerbations and the impact of these events in patients with progressive pulmonary fibrosis. Methods Patients with progressive fibrosing ILDs other than idiopathic pulmonary fibrosis (IPF) were randomised to receive nintedanib or placebo. Associations between baseline characteristics and time to first acute exacerbation were assessed using pooled data from both treatment groups using Cox proportional hazard models, firstly univariable models and then a multivariable model using forward stepwise selection. The risk of death was estimated based on the Kaplan−Meier method. Results Over a median follow-up of approximately 19 months, acute exacerbations were reported in 58 (8.7%) of 663 patients. In the risk factor analysis, the final model included diffusing capacity of the lung for carbon monoxide (DLCO) % predicted, treatment and age. Lower DLCO % predicted was associated with an increased risk of acute exacerbation with a hazard ratio (HR) of 1.56 (95% CI 1.21–2.02) per 10 units lower (p<0.001). Age ≥65 years was associated with a numerically increased risk (HR 1.55, 95% CI 0.87–2.77; p=0.14). Treatment with nintedanib conferred a numerically reduced risk versus placebo (HR 0.60, 95% CI 0.35–1.02; p=0.06). The estimated risks of death ≤30 days and ≤90 days after an acute exacerbation were 19.0% (95% CI 8.9–29.2) and 32.0% (95% CI 19.7–44.2). Conclusions Acute exacerbations of progressive pulmonary fibrosis may have similar risk factors and prognostic impact as acute exacerbations of IPF.