PLoS Genetics (Nov 2022)
Exome-wide association study to identify rare variants influencing COVID-19 outcomes: Results from the Host Genetics Initiative.
- Guillaume Butler-Laporte,
- Gundula Povysil,
- Jack A Kosmicki,
- Elizabeth T Cirulli,
- Theodore Drivas,
- Simone Furini,
- Chadi Saad,
- Axel Schmidt,
- Pawel Olszewski,
- Urszula Korotko,
- Mathieu Quinodoz,
- Elifnaz Çelik,
- Kousik Kundu,
- Klaudia Walter,
- Junghyun Jung,
- Amy D Stockwell,
- Laura G Sloofman,
- Daniel M Jordan,
- Ryan C Thompson,
- Diane Del Valle,
- Nicole Simons,
- Esther Cheng,
- Robert Sebra,
- Eric E Schadt,
- Seunghee Kim-Schulze,
- Sacha Gnjatic,
- Miriam Merad,
- Joseph D Buxbaum,
- Noam D Beckmann,
- Alexander W Charney,
- Bartlomiej Przychodzen,
- Timothy Chang,
- Tess D Pottinger,
- Ning Shang,
- Fabian Brand,
- Francesca Fava,
- Francesca Mari,
- Karolina Chwialkowska,
- Magdalena Niemira,
- Szymon Pula,
- J Kenneth Baillie,
- Alex Stuckey,
- Antonio Salas,
- Xabier Bello,
- Jacobo Pardo-Seco,
- Alberto Gómez-Carballa,
- Irene Rivero-Calle,
- Federico Martinón-Torres,
- Andrea Ganna,
- Konrad J Karczewski,
- Kumar Veerapen,
- Mathieu Bourgey,
- Guillaume Bourque,
- Robert Jm Eveleigh,
- Vincenzo Forgetta,
- David Morrison,
- David Langlais,
- Mark Lathrop,
- Vincent Mooser,
- Tomoko Nakanishi,
- Robert Frithiof,
- Michael Hultström,
- Miklos Lipcsey,
- Yanara Marincevic-Zuniga,
- Jessica Nordlund,
- Kelly M Schiabor Barrett,
- William Lee,
- Alexandre Bolze,
- Simon White,
- Stephen Riffle,
- Francisco Tanudjaja,
- Efren Sandoval,
- Iva Neveux,
- Shaun Dabe,
- Nicolas Casadei,
- Susanne Motameny,
- Manal Alaamery,
- Salam Massadeh,
- Nora Aljawini,
- Mansour S Almutairi,
- Yaseen M Arabi,
- Saleh A Alqahtani,
- Fawz S Al Harthi,
- Amal Almutairi,
- Fatima Alqubaishi,
- Sarah Alotaibi,
- Albandari Binowayn,
- Ebtehal A Alsolm,
- Hadeel El Bardisy,
- Mohammad Fawzy,
- Fang Cai,
- Nicole Soranzo,
- Adam Butterworth,
- COVID-19 Host Genetics Initiative,
- DeCOI Host Genetics Group,
- GEN-COVID Multicenter Study (Italy),
- Mount Sinai Clinical Intelligence Center,
- GEN-COVID consortium (Spain),
- GenOMICC Consortium,
- Japan COVID-19 Task Force,
- Regeneron Genetics Center,
- Daniel H Geschwind,
- Stephanie Arteaga,
- Alexis Stephens,
- Manish J Butte,
- Paul C Boutros,
- Takafumi N Yamaguchi,
- Shu Tao,
- Stefan Eng,
- Timothy Sanders,
- Paul J Tung,
- Michael E Broudy,
- Yu Pan,
- Alfredo Gonzalez,
- Nikhil Chavan,
- Ruth Johnson,
- Bogdan Pasaniuc,
- Brian Yaspan,
- Sandra Smieszek,
- Carlo Rivolta,
- Stephanie Bibert,
- Pierre-Yves Bochud,
- Maciej Dabrowski,
- Pawel Zawadzki,
- Mateusz Sypniewski,
- Elżbieta Kaja,
- Pajaree Chariyavilaskul,
- Voraphoj Nilaratanakul,
- Nattiya Hirankarn,
- Vorasuk Shotelersuk,
- Monnat Pongpanich,
- Chureerat Phokaew,
- Wanna Chetruengchai,
- Katsushi Tokunaga,
- Masaya Sugiyama,
- Yosuke Kawai,
- Takanori Hasegawa,
- Tatsuhiko Naito,
- Ho Namkoong,
- Ryuya Edahiro,
- Akinori Kimura,
- Seishi Ogawa,
- Takanori Kanai,
- Koichi Fukunaga,
- Yukinori Okada,
- Seiya Imoto,
- Satoru Miyano,
- Serghei Mangul,
- Malak S Abedalthagafi,
- Hugo Zeberg,
- Joseph J Grzymski,
- Nicole L Washington,
- Stephan Ossowski,
- Kerstin U Ludwig,
- Eva C Schulte,
- Olaf Riess,
- Marcin Moniuszko,
- Miroslaw Kwasniewski,
- Hamdi Mbarek,
- Said I Ismail,
- Anurag Verma,
- David B Goldstein,
- Krzysztof Kiryluk,
- Alessandra Renieri,
- Manuel A R Ferreira,
- J Brent Richards
Affiliations
- Guillaume Butler-Laporte
- Gundula Povysil
- Jack A Kosmicki
- Elizabeth T Cirulli
- Theodore Drivas
- Simone Furini
- Chadi Saad
- Axel Schmidt
- Pawel Olszewski
- Urszula Korotko
- Mathieu Quinodoz
- Elifnaz Çelik
- Kousik Kundu
- Klaudia Walter
- Junghyun Jung
- Amy D Stockwell
- Laura G Sloofman
- Daniel M Jordan
- Ryan C Thompson
- Diane Del Valle
- Nicole Simons
- Esther Cheng
- Robert Sebra
- Eric E Schadt
- Seunghee Kim-Schulze
- Sacha Gnjatic
- Miriam Merad
- Joseph D Buxbaum
- Noam D Beckmann
- Alexander W Charney
- Bartlomiej Przychodzen
- Timothy Chang
- Tess D Pottinger
- Ning Shang
- Fabian Brand
- Francesca Fava
- Francesca Mari
- Karolina Chwialkowska
- Magdalena Niemira
- Szymon Pula
- J Kenneth Baillie
- Alex Stuckey
- Antonio Salas
- Xabier Bello
- Jacobo Pardo-Seco
- Alberto Gómez-Carballa
- Irene Rivero-Calle
- Federico Martinón-Torres
- Andrea Ganna
- Konrad J Karczewski
- Kumar Veerapen
- Mathieu Bourgey
- Guillaume Bourque
- Robert Jm Eveleigh
- Vincenzo Forgetta
- David Morrison
- David Langlais
- Mark Lathrop
- Vincent Mooser
- Tomoko Nakanishi
- Robert Frithiof
- Michael Hultström
- Miklos Lipcsey
- Yanara Marincevic-Zuniga
- Jessica Nordlund
- Kelly M Schiabor Barrett
- William Lee
- Alexandre Bolze
- Simon White
- Stephen Riffle
- Francisco Tanudjaja
- Efren Sandoval
- Iva Neveux
- Shaun Dabe
- Nicolas Casadei
- Susanne Motameny
- Manal Alaamery
- Salam Massadeh
- Nora Aljawini
- Mansour S Almutairi
- Yaseen M Arabi
- Saleh A Alqahtani
- Fawz S Al Harthi
- Amal Almutairi
- Fatima Alqubaishi
- Sarah Alotaibi
- Albandari Binowayn
- Ebtehal A Alsolm
- Hadeel El Bardisy
- Mohammad Fawzy
- Fang Cai
- Nicole Soranzo
- Adam Butterworth
- COVID-19 Host Genetics Initiative
- DeCOI Host Genetics Group
- GEN-COVID Multicenter Study (Italy)
- Mount Sinai Clinical Intelligence Center
- GEN-COVID consortium (Spain)
- GenOMICC Consortium
- Japan COVID-19 Task Force
- Regeneron Genetics Center
- Daniel H Geschwind
- Stephanie Arteaga
- Alexis Stephens
- Manish J Butte
- Paul C Boutros
- Takafumi N Yamaguchi
- Shu Tao
- Stefan Eng
- Timothy Sanders
- Paul J Tung
- Michael E Broudy
- Yu Pan
- Alfredo Gonzalez
- Nikhil Chavan
- Ruth Johnson
- Bogdan Pasaniuc
- Brian Yaspan
- Sandra Smieszek
- Carlo Rivolta
- Stephanie Bibert
- Pierre-Yves Bochud
- Maciej Dabrowski
- Pawel Zawadzki
- Mateusz Sypniewski
- Elżbieta Kaja
- Pajaree Chariyavilaskul
- Voraphoj Nilaratanakul
- Nattiya Hirankarn
- Vorasuk Shotelersuk
- Monnat Pongpanich
- Chureerat Phokaew
- Wanna Chetruengchai
- Katsushi Tokunaga
- Masaya Sugiyama
- Yosuke Kawai
- Takanori Hasegawa
- Tatsuhiko Naito
- Ho Namkoong
- Ryuya Edahiro
- Akinori Kimura
- Seishi Ogawa
- Takanori Kanai
- Koichi Fukunaga
- Yukinori Okada
- Seiya Imoto
- Satoru Miyano
- Serghei Mangul
- Malak S Abedalthagafi
- Hugo Zeberg
- Joseph J Grzymski
- Nicole L Washington
- Stephan Ossowski
- Kerstin U Ludwig
- Eva C Schulte
- Olaf Riess
- Marcin Moniuszko
- Miroslaw Kwasniewski
- Hamdi Mbarek
- Said I Ismail
- Anurag Verma
- David B Goldstein
- Krzysztof Kiryluk
- Alessandra Renieri
- Manuel A R Ferreira
- J Brent Richards
- DOI
- https://doi.org/10.1371/journal.pgen.1010367
- Journal volume & issue
-
Vol. 18,
no. 11
p. e1010367
Abstract
Host genetics is a key determinant of COVID-19 outcomes. Previously, the COVID-19 Host Genetics Initiative genome-wide association study used common variants to identify multiple loci associated with COVID-19 outcomes. However, variants with the largest impact on COVID-19 outcomes are expected to be rare in the population. Hence, studying rare variants may provide additional insights into disease susceptibility and pathogenesis, thereby informing therapeutics development. Here, we combined whole-exome and whole-genome sequencing from 21 cohorts across 12 countries and performed rare variant exome-wide burden analyses for COVID-19 outcomes. In an analysis of 5,085 severe disease cases and 571,737 controls, we observed that carrying a rare deleterious variant in the SARS-CoV-2 sensor toll-like receptor TLR7 (on chromosome X) was associated with a 5.3-fold increase in severe disease (95% CI: 2.75-10.05, p = 5.41x10-7). This association was consistent across sexes. These results further support TLR7 as a genetic determinant of severe disease and suggest that larger studies on rare variants influencing COVID-19 outcomes could provide additional insights.